Defects in UNC13d are a cause of familial hemophagocytic lymphohistiocytosis type 3 (FHL3). FHL3 is phenotypically homogeneous and indistinguishable from HPLH2/FHL2. Patients have a nonmalignant accumulation and multivisceral infiltration of activated T lymphocytes and histiocytes (macrophages). Familial hemophagocytic lymphohistiocytosis is a genetically heterogeneous condition characterized by defective cytotoxicity.
Alternative names
HPLH3
FHL3
Familial erythrophagocytic lymphohistiocytosis type 3
Familial histiocytic reticulosis 3
Hemophagocytic lymphohistiocytosis
Hemophagocytic lymphohistiocytosis/UNC13D
Classification
- Defects of phagocyte function
- Familial haemophagocytic lymphohistiocytosis, FHL3
Inheritance
Autosomal recessive
Cross references
Phenotypically related immunodeficiencies
IDR factfile for Familial haemophagocytic lymphohistiocytosis type 1
IDR factfile for Familial haemophagocytic lymphohistiocytosis type 2
Incidence
1:50,000 births